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CEREBELLUM/ TRACTS

SENSORY MOTOR NEUROPATHY

OCULOMOTOR APRAXIA 

ATAXIA TELANGIECTASIA

TELENGIECTASIA  OVER

EYES/ SUN EXPOSED AREAS

OCULOMOTOR APRAXIA/ HYPOMETRIC 

DYSTONIA/ CHOREA/ MYOCLONUS

PARKINSONISM/ ATAXIA / TREMOR/ NEUROPATHY

LYMPHOMA/ LEUKEMIA (EARLY)

SOLID TUMOUR (LATE)

LAB: LOW IGA/ IGG

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AOA1 (APTX)

AGE OF ONSET 2-10YRS

OCULOMOTOR APRAXIA

DYSTONIA/ CHOREA/ ATAXIA

NEUROPATHY

LAB: ALBUMIN REDUCED

TOTAL CHOLESTEROL INCREASED

NORMAL ALFA FETO-PROTEIN

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AOA2 (SETX)

AGE OF ONSET 3-30YRS

OCULOMOTOR APRAXIA

DYSTONIA/ CHOREA/ ATAXIA

NEUROPATHY

LAB: ALBUMIN REDUCED

TOTAL CHOLESTEROL INCREASED

INCREASED IGA/ IGG/ ALPA FETO-PROTEIN

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MITOCHONDRIAL

POLG1 (NUCLEAR DNA)

MIRAS (POLG1)

CHILDHOOD: ENCEPHALOPATHY

JUVENILE: EPILEPSY/ MIGRAINE

ADULT ONSET: ATAXIA NEUROPATHY

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SANDOS (POLG1)

SENSORY ATAXIA/ DYSARTHRIA/ OPHTHALMOPLEGIA

PARKINSONISM

COMPOUND  HETEROZYGOUS MUTATION CAN HAVE LATE PRESENTATION, 80YRS

 

MEMSA (POLG1)

MYOCLONIC EPILEPSY/ MYOPATHY 

SENSORY ATAXIA

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MINGIE (POLG1)

MITOCHONDRIAL NEUROGASTROINTESTINAL ENCEPHALOPATHY

GASTROPARESIS/ ATAXIA

NEUROPATHY/ MYOPATHY

LEUKOENCEPHALOPATHY

OPTHALMOPARESIS/ PTOSIS

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SCAE (POLG1)

OLD TERMINOLOGY

NOW INCLUDES MEMSA

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MITOCHONDRIAL DNA

LEIGH SYNDROME

MITOCHONDRIAL/ NUCLEAR GENES INVOLVED IN OXIDATIVE PHOSPHORYLATION (COMPLEX 1-4)

COGNITION/ ATAXIA/CHOREA

OPTIC ATROPHY/ RETINITIS PIGMENTOSA

STRABISMUS/ OPHTHALMOPARESIS

NEUROPATHY/ MYOPATHY

SHORT STATURE/ CARDIOMYOPATHY

ADULT ONSET SUBACUTE NECROTIZING ENCEPHALOPATHY:

VISION PROBLEM/ ATAXIA

SENSORY NEUROPATHY

FRIEDREICH'S ATAXIA (FXN) 

ATAXIA/ DYSRTHRIA/  SCOLIOSIS

DIABETES (30%)

HEARING LOSS (20%)

HYPERTROPHIC CARDIOMYOPATHY ARRHYTHMIA/ CHF

LOFA 25-40YRS

VLOFA >40YRS

MRI: CEREBELLAR ATROPHY LATE STAGES

SPINAL CORD ATROPHY

DENTATE IRON ACCUMULATION AND ATROPHY 

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ABETALIPOPROTEINAEMIA (MTTP)

DIARRHOEA/ VIT-E/ VIT-D/ VIT-K DEFICIENCY

ATAXIA/ PERIPHERAL NEUROPATHY

RETINITIS PIGMENTOSA

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ATAXIA WITH VITAMIN E DEFICIENCY (TTPA)

VIT-E DEFICIENCY

TITUBATION

ATAXIA/ PERIPHERAL NEUROPATHY

RETINITIS PIGMENTOSA/ MACULAR ATROPHY

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CANVAS (RFC1-AAGGG)  

AGE OF ONSET <50YRS

CEREBELLAR/ VESTIBULAR/ SENSORY ATAXIA

ABNORMAL VVOR AND PURSUIT

ABNORMAL VVOR : 

HEAD MOVED AT 0.5HZ WITH VISION FIXED AT EARTH FIXED TARGET. SACCADIC EYE MOVEMENTS SEEN AS VESTIBULAR AND PURSUIT BOTH ARE ABNORMAL

SENSORY MOTOR NEUROROPATHY 

GANGLIONOPATHY

COUGH/AUTONOMIC DYSFUNCTION

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DEMYELINATING NEUROPATHY 

REFSUM (PHYN/PEX7)  

DEAFNESS/ ANOSMIA

RETINITIS PIGMENTOSA

ICHTHIOSIS/ SENSORY NEUROPATHY

DEMYELINATING NEUROPATHY

PLASMA PHYTANIC ACID LEVELS RAISED

RX: AVOID PHYTANIC ACID

HIGH CALORIC DIET, PREVENT MOBILIZATION OF PHYTANIC ACID FOR ADIPOSE TISSUE

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SCP2 MUTATIONS 

FOCAL OMD/ TORTICOLLIS

ATAXIA/ DYSTONIA/ MOTOR NEUROPATHY

MRI: CEREBRAL/ PONS WHITE MATTER HYPERINTENSITY

BASAL GANGLIA IRON DEPOSITION

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BASAL GANGLIA

BRAIN MINERALIZATION DISORDERS

MPAN 

DYSTONIA/ PARKINSONISM

SPASTICITY

BILATERAL OPTIC ATROPHY

AXONAL NEUROPATHY

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COPAN (COASY) 

SLOWLY PROGRESSIVE

DYSTONIA/ PARKINSONISM

SPASTICITY/ AXONAL NEUROPATHY

MRI: EYE OF TIGER SIGN 

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NEUROACANTHOCYTOSIS SYNDROMES

CHOREA-ACANTHOCYTOSIS (VPS13A)

AGE OF ONSET 20-60YRS

ACTION TONGUE DYSTONIA

FEEDING DYSTONIA/ TICS

RUBBER-MAN GAIT/DROP ATTACK

NEUROPATHY/ MYOPATHY

PSYCHIATRIC MANIFESTATIONS/ SEIZURE 

HEPATO-SPLEENOMEGALY

LAB:  CPK/ LFT ELEVATED

ACANTHOCYTES TO BE SEEN IN 1:1 DILUTION IN NORMAL SALINE WITH PHASE CONTRAST MICROSCOPE

ACANTHOCYTE CAN BE ABSENT

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CORTICAL/ SUBCORTICAL

PELIZAEUS MERZBACHER DISEASE (PLP1)

SPASTIC ATAXIA 

SPG2: PURE SPASTIC PARAPARESIS

MULTIFOCAL DEMYELINATING NEUROPATHY

COGNITION/ TITUBATION 

DYSTONIA/ CHOREA OF EXTREMITIES

HEAD AND UPPER LIMB TREMOR

SURVIVAL TILL LATE ADULTHOOD

MRI: HYPOMYELINATION

INTERNAL CAPSULE/ OPTIC RADIATION

PROXIMAL CORONAL RADIATA

CEREBELLAR ATROPHY

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